Title: Pleomorphic Adenoma of minor Salivary Gland arising from Thyroglossal Duct: Uncommon Presentation
Authors: Dr Digant Patni, Dr Shivprakash Mehta, Dr Auran Dehadaray, Dr Maitri Kaushik
DOI: https://dx.doi.org/10.18535/jmscr/v7i7.149
Abstract
Introduction: Patent thyroglossal tract commonly appears as a midline neck swelling in form of Thyroglossal cyst. Presentation in form of pleomorphic adenoma has not yet been reported. The aim of this study is to present a case of clinically appearing as thyroglossal cyst which was reported as pleomorphic adenoma of minor salivary gland.
Case Report: A 40 year old lady presented with midline neck swelling in suprahyoid region. Welling moved with deglutination and protrusion of tongue. Intraoperatively there was a fibrous band which attached the cyst through the hyoid bone to the tongue. Complete swelling was removed with body of hyoid bone and was sent for histopathology examination (HPE).
Results: HPE of the mass revealed pleomorphic adenoma of minor salivary gland arising from thyroglossal duct. Literature search does not show any such evidence of pleomorphic adenoma arising from thyroglossal duct.
Conclusion: Midline neck swelling which clinically appears a Thyroglossal cyst may rarely be pleomorphic adenoma.
Keywords: Neck swelling, Thyroglossal cyst , Pleomorphic adenoma ,midline neck swelling, salivary gland tumour.
References
- Spiro RH: Salivary Neoplasms: overview of a 35 year experience with 2807 patients. Head Neck Surgery 1986, 8:1777-84
- Peng and G.Har-El, “Anatomy and physiology”, in Essentials of Otolaryngology , FE. Lucente and G. Har-El, Eds,pp. 3-39 Lippincott Williams &Wilikins, Philadelphia, Pa,USA,5th edition ,2004.
- Eveson JW, Cawson RA: Tumour of the minor (orophparyngeal) salivary glands: demographic study of 336 cases.J Oral Pathol. 1985, 14:500-509
- M Paparella and D.A.Shumrick, Otolaryngology, W.B. Saunders, Philadelphia, Pa,USA,3rd edition,1991
- M Speight and A.W.Barrett, “Salivary gland tumours” Oral Diseases. 2002; 8(5): 229-40.
- R. Gnepp, “Malignant mixed tumours” in Surgical Pathology of salivary glands, B.V. Eliss, P.L .Auclair ,and D.R.Gnepp, Eds.,pp.350-368,W.B Saunders, Philadelphia, Pa, USA,1991.
- G. Batsakis, “Tumours of the major salivary glands ,” in Tumours of Head and Neck, p.22, Williams & Wilkins, Baltimore , Md , USA,2nd edition,1978
- Vegari et al. Pleomorphic Adenoma of the Cervical Heterotopic Salivary Gland: A Case Report. Case Rep Otolaryngol. 2012:470652.
- Laturiya et al. Pleomorphic Adenoma of Minor Salivary Gland Arising de novo in the Parapharyngeal Space-A Rare Case Report. Journal of Clinical and Diagnostic Research. 2016 Mar, Vol-10(3): ZD01-ZD03
- Testa D, Staibano S, Guerra G, Mascolo M, GaleraF, Iovine R, et al. Pleomorphic adenoma in ectopic salivary tissue of the neck. The Open Otorhinolaryngology Journal. 2008;2:3-5.
- Arunkumar KV, Kumar S, Bansal V, Saxena S,Elhence P. Pleomorphic adenoma – unusual presentation of a salivary glandtumour in the neck of a child. Quintessence International. 2011;42(10):879-82.
- Hashizume et al. Mid-cervical malignant pleomorphic adenoma presenting with upper airway obstruction. Acta Paediatr Jpn. 1990 Oct;32(5):559-62
- Kamath B, Kamath P,Bhukebag P. Pleomorphic Adenoma in Subcutaneous Plane of the Neck: A Rare Entity .Journal of Clinical and Diagnostic Research. 2015 Sep, Vol-9(9): PD24 PD25.