Title: Congenital Cystic Adenomatoid Malformation: Case Report
Authors: Mohammed Junaid Ansari, *Shahla Abrar, Tanvir Roshan Khan
DOI: http://dx.doi.org/10.18535/jmscr/v4i3.26
Congenital Cystic Adenomatoid Malformation (CCAM) is a rare development abnormality of the lung occurring in 1- 4 / 100,000 live birth.it is often confused with pneumatocoele or pneumothorax which are common in developing countries. We report here a case of 5 months old baby with features of respiratory distress since birth and CECT thorax suggestive of large cystic lesion of left lung i.e., CCAM. Keywords - CCAM , rare, Cystic lesion , Respiratory distress. 1. Godwin JD, Webb WR, Savoca CJ, Gamsu G, Goodman PC. Multiple, thin-walled cystic lesions of the lung. AJR Am J Roentgenol. 1980;135:593–604. 2. Dillman JR, Sanchez R, Ladino-Torres MF, Yarram SG, Strouse PJ, Lucaya J. Expanding upon the unilateral hyperlucent hemithorax in children radiographics, 2011 31:723–41. 3. Visrutaratna P, Euathrongchit J, Kattipattanapong V. Clinics in diagnostic imaging (86). Ruptured bronchogenic cyst. Singapore Med J. 2003;44:325–9. 4. Schwartz MZ, Ramachandran P. Congenital malformations of the lung and mediastinum-a quarter century of experience from a single institution. J Pediatr Surg. 1997;32:44–7. 5. Kunyoshi V, Cataneo D, Cataneo A. Complicated pneumonias with empyema and/or pneumatocele in children. Pediatr Surg Int. 2006;22:186–90. 6. Chi’n KY, Tang MY. Congenital cystic adenomatoid malformation of one lobe of a lung with general anasarca. Arch Pathol 1949; 48: 221-229. 7. Laberge JM, Flageole H, Pugash D, Khalife S, Blair G, Filiatrault D, et al. Outcome of the prenatally diagnosed CCAM: a Canadian experience. Fetal Diagn Ther 2001;16(3):178-86. 8. Sindhwani G, Whig J, Gupta A, Rawat J. Tuberculosis in congeniatal adenomatoid malformation: a rare presentation. Lung India 2007;24(4):148-9. 9. Luján M, Bosque M, Mirapeix RM, Marco MT, Asensio O, Domingo C. Late onset congenital cystic adenomatoid malform-ation of the lung. Embryology, clinical symptomatology, diagnostic procedures, therapeutic approach and clinical follow-up. Respiration2002;69(2):148-54. 10. Parikh D, Samuel M. Congenital cystic lung lesions: is surgical resection essential? Padiatr Pulmonol 2005; 40(6): 533-7. 11. Cass DL, Olutoye OO, Cassady CI, Moise KJ, Johnson A, Papanna R, et al. Prenatal diagnosis and outcome of fetal lung masses. J Pediatr Surg. 2011;46:292–8. 12. Zeidan S, Hery G, Lacroix F, Gorincour G, Potier A, Dubus JC, et al. Intralobar sequestration associated with cystic adenomatoid malformation: Diagnostic and thoracoscopic pitfalls. Surg Endosc. 2009;23:1750–3. 13. Belcher E, Lawson MH, Nicholson AG, Davison A, Goldstraw P. Congenital cystic adenomatoid malformation presenting as in-flight systemic air embolisation. Eur Respir J. 2007;30:801–4. 14. Sahu S, Muthuvel S, Naware SS, Dhavala SS. Congenital cystic adenomatoid malformation of lung. Med J Armed Forces India. 2008;64:268–9. 15. Stocker JT, Madewell JE, Drake RM. Congenital cystic adenomatoid malformation of the lung. Classification and morphologic spectrum. Hum Pathol 1977;8:155‑71. 16. Nandi M, Mondal R. Congenital cystic disorders of lung masquerading as complicated pneumonia and pneumothorax: A case series. Eastern J Med 2010;15:125‑7. 17. Kumar B, Agrawal LD, Sharma SB. Congenital bronchopulmonary malforma-tions: A single‑center experience and a review of literature. Ann Thorac Med 2008;3:135‑9. 18. Feng A, Cai H, Sun Q, Zhang Y, Chen L, Meng F. Congenital cystic adenomatoid malformation of lung in adults: 2 rare cases report and review of the literature. Diagn Pathol. 2012;7:37. 19. Belcher E, Lawson MH, Nicholson AG, Davison A, Goldstraw P. Congenital cystic adenomatoid malformation presenting as in-flight systemic air embolisation. Eur Respir J. 2007;30:801–4. 20. Loachimescu OC, Mehta AC. From cystic pulmonary airway malformation, to bronchioloalveolar carcinoma and adenocarcinoma of the lung. Eur Respir J. 2005;26:1181–7. 21. Weinblatt ME, Siegel SE, Isaacs H. Pulmonary blastoma associated with cystic lung disease. Cancer 1982; 49: 669-671. 22. Filler J. Effects upon pulmonary function of lobectomy performed during childhood. Am Rev Respir Dis 1964; 89: 801-810. 23. Peters RM, Wilcox BR, Schultz EH. Pulmonary resection in children: Long-term effect on function and lung growth. Ann Surg 1964; 159: 652-660.Abstract
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