Title: Unilateral Pulmonary Hypoplasia in an Adult Nigerian: A Case Report and Literature Review

Authors: Tsavyange Peter Mbaave, Annongu Isaac Terkimbi, Ihunaya Chinyere Okpara

 DOI: https://dx.doi.org/10.18535/jmscr/v7i6.104

Abstract

Background: Pulmonary hypoplasia presenting for the first time in adulthood is rare and can pose a diagnostic challenge without a high index of suspicion and proper investigations.

Materials and Method: We present a 42 year old man with an initial diagnosis of lung fibrosis from pulmonary tuberculosis but who on further evaluation was found to have left pulmonary hypoplasia. The history and clinical examination findings and are presented and management discussed. The patient was treated with empirical antibiotics, bronchodilators and referred for surgical evaluation.

Pulmonary hypoplasia should be suspected in adults with homogenous opacification of the hemithorax.

Keywords: computed tomography, hypoplasia, pulmonary, unilateral

References

  1. Aristida Georgescu, Crinu Nuta, and Simona Bondari, “3D Imaging in Unilateral Primary Pulmonary Hypoplasia in an Adult: A Case Report,” Case Reports in Radiology, vol. 2011,Article ID 659586, 6 pages, 2011. https://doi.org/10.1155/2011/659586.
  2. Vishnukanth Govindaraj, Manju R, Srinivas Banoth, Pratap Upadhaya. Isolated left lung hypoplasia in an adult- A case report.  Int J Cur Res Rev | Vol 6 • Issue 15 • August 2014
  3. Katsenos S., Antonogiannaki E.-M., Tsintiris K Unilateral primary lung hypoplasia diagnosed in adulthood. Respiratory Care April 2014, 59 (4) e47-e50; DOI: https://doi.org/10.4187/respcare.02740
  4. Figen Gülen1, Sakine Kar1, Levent Midyat1*, Esen Demir1, Süphan Özyurt2, Arif Ruhi Özyürek3, Remziye Tanaç1, Naim Ceylan4.A rare clinical presentation of pulmonary hypoplasia. Open Journal of Pediatrics, 2011, 1, 75-78 doi:10.4236/ojped.2011.14018 Published Online December 2011 (http://www.SciRP.org/journal/ojped/
  5. Shah AA, Singh AR, Kharat AT. Unilateral pulmonary hypoplasia in an adult . Med J DY Patil Univ [serial online] 2016 [cited 2019 May 24];9:110-3. Available from: http://www.mjdrdypu.org/text.asp?2016/9/1/110/167971
  6. Singh U, Mohan V, Goyal D.K, Ramaraj M, Shailly, Poduvattil P, Kaur R.P, Abraham J. Hypoplasia of lung a rare entity mimicking as a case of tuberculosis. Int J Med Res Rev 2017;5(03):315-319 doi:10.17511/ijmrr. 2017.i03.16.
  7. Komolafe F, Dahniya MH, Al-Ali Y, Al-Zaabi L, Aziz F. Asymptomatic unilateral pulmonary hypoplasia/agenesis in adults: A report of six cases. West Afr J Radiol [serial online] 2017 [cited 2019 May 23];24:99-103. Available from:  http://www.wajradiology.org/text.asp?2017/24/1/99/198151
  8. Pathania M, Lali BS, Rathaur VK. Unilateral pulmonary hypoplasia: a rare clinical presentation. BMJ Case Rep. 2013 Mar 20; 2013. pii: bcr2012008098. doi: 10.1136/bcr-2012-008098.
  9. Kavita Paul, Aman Bharti, Harbans Lal Kazal. Unilateral Lung Hypoplasia Presenting in Adolescence: A Case Report. Journal of Evolution of Medical and Dental Sciences 2015; Vol. 4, Issue 56, July 13; Page: 9842-9845, DOI: 10.14260/jemds/2015/142
  10. Lin, Shan, MM; Guan, Wei, MD*; LaZhou, CuoMao, MM; Shi, Yingqing, MM. Left lung hypoplasia with a right tuberculous pleural effusion after childbirth A case report .Medicine: May 2018 - Volume 97 - Issue 21 - p e10868 doi: 10.1097/MD.0000000000010868.

Corresponding Author

Dr Tsavyange Peter Mbaave

Department of Medicine, College of Health Sciences, Benue State University Makurdi, Nigeria